A unique case of recurrent Intracranial Extravascular Papillary Endothelial Hyperplasia following gross total resection and brachytherapy.

•Extravascular papillary endothelial hyperplasia is an extremely rare pathology that appears to be linked to prior radiosurgery.•To date, there have been no reported cases of EPEH recurrence after gross total resection.•This case report is the first known recurrence of intracranial EPEH occurring after gross total resection and brachytherapy.•EPEH incidence will likely increase as combination surgery and radiation becomes the standard for many CNS neoplasms.